Tuberous sclerosis complex (TSC) is a rare genetic disorder characterized by the formation of benign tumors in various organs, particularly in the central nervous system. We aimed to delineate the molecular profile of Turkish individuals diagnosed with TSC by analyzing the TSC1 and TSC2 genes using next-generation sequencing (NGS). Sophia Genetics' Sophia Inherited Disease Panel was used to perform NGS on 22 individuals diagnosed with TSC and to identify pathogenic variants in the TSC1 and TSC2 genes. Among the 22 cases, mutations were found in 3 (13.6%) for TSC1 and in 16 (73%) for TSC2, while 3 (13.6%) exhibited no detectable mutations. Notably, one individual with a TSC2 mutation presented with angiofibroma, ungual fibroma, and pitted dental enamel, while another had cardiac rhabdomyoma. Autism spectrum disorders were observed in 6 (27%) with TSC2 mutations, including one with autistic behavior. Abnormal motor development was noted in 3 (13.6%), of which 2 had TSC2 mutations. Severe intellectual disability was found in 3 (13.6%) with TSC2 mutations, and developmental delay was seen in 2 (9%) with TSC2 mutations. Epileptic encephalopathy occurred in 3 (13.6%), with 2 having TSC2 mutations. Additionally, 6 (27%) exhibited drug resistance for focal seizures, with 5 of them having TSC2 mutations. These findings are consistent with other research indicating that TSC2 mutations are associated with a more severe phenotypic range compared to TSC1 mutations. Moreover, our analysis showed that some people with TSC1/TSC2 mutations did not match diagnostic criteria. This highlights the importance of genetic testing and molecular profiling in understanding the clinical variability and aiding in the management of TSC patients.
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Univ Roma Tor Vergata, Pediat Neurol Unit, Dept Neurosci, I-00133 Rome, ItalyUniv Roma Tor Vergata, Pediat Neurol Unit, Dept Neurosci, I-00133 Rome, Italy
Curatolo, Paolo
Bombardieri, Roberta
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Univ Roma Tor Vergata, Pediat Neurol Unit, Dept Neurosci, I-00133 Rome, ItalyUniv Roma Tor Vergata, Pediat Neurol Unit, Dept Neurosci, I-00133 Rome, Italy
Bombardieri, Roberta
Jozwiak, Sergiusz
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Childrens Mem Hlth Inst, Dept Neurol & Epileptol, Warsaw, PolandUniv Roma Tor Vergata, Pediat Neurol Unit, Dept Neurosci, I-00133 Rome, Italy
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Univ Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South AfricaUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
de Vries, Petrus J.
Whittemore, Vicky H.
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NINDS, NIH, Bethesda, MD 20892 USAUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
Whittemore, Vicky H.
Leclezio, Loren
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Univ Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South AfricaUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
Leclezio, Loren
Byars, Anna W.
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Univ Cincinnati, Coll Med, Cincinnati Childrens Hosp Med Ctr, Cincinnati, OH USAUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
Byars, Anna W.
Dunn, David
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Indiana Univ Sch Med, Riley Child & Adolescent Psychiat Clin, Indianapolis, IN 46202 USAUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
Dunn, David
Ess, Kevin C.
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Vanderbilt Univ, Ctr Med, Dept Pediat, Div Pediat Neurol, Nashville, TN 37232 USAUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
Ess, Kevin C.
Hook, Dena
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TB Sclerosis Alliance, Silver Spring, MD USAUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
Hook, Dena
King, Bryan H.
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Univ Washington, Dept Psychiat & Behav Sci, Seattle, WA 98195 USA
Seattle Childrens Hosp, Seattle, WA USAUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
King, Bryan H.
Sahin, Mustafa
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Boston Childrens Hosp, FM Kirby Ctr Neurosci, Dept Neurol, Boston, MA USAUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
Sahin, Mustafa
Jansen, Anna
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VUB, Dept Publ Hlth, UZ Brussel, Pediat Neurol Unit, Brussels, BelgiumUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
机构:
Univ Roma Tor Vergata, Pediat Neurol Unit, Dept Neurosci, I-00133 Rome, ItalyUniv Roma Tor Vergata, Pediat Neurol Unit, Dept Neurosci, I-00133 Rome, Italy
Curatolo, Paolo
Bombardieri, Roberta
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机构:
Univ Roma Tor Vergata, Pediat Neurol Unit, Dept Neurosci, I-00133 Rome, ItalyUniv Roma Tor Vergata, Pediat Neurol Unit, Dept Neurosci, I-00133 Rome, Italy
Bombardieri, Roberta
Jozwiak, Sergiusz
论文数: 0引用数: 0
h-index: 0
机构:
Childrens Mem Hlth Inst, Dept Neurol & Epileptol, Warsaw, PolandUniv Roma Tor Vergata, Pediat Neurol Unit, Dept Neurosci, I-00133 Rome, Italy
机构:
Univ Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South AfricaUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
de Vries, Petrus J.
Whittemore, Vicky H.
论文数: 0引用数: 0
h-index: 0
机构:
NINDS, NIH, Bethesda, MD 20892 USAUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
Whittemore, Vicky H.
Leclezio, Loren
论文数: 0引用数: 0
h-index: 0
机构:
Univ Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South AfricaUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
Leclezio, Loren
Byars, Anna W.
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h-index: 0
机构:
Univ Cincinnati, Coll Med, Cincinnati Childrens Hosp Med Ctr, Cincinnati, OH USAUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
Byars, Anna W.
Dunn, David
论文数: 0引用数: 0
h-index: 0
机构:
Indiana Univ Sch Med, Riley Child & Adolescent Psychiat Clin, Indianapolis, IN 46202 USAUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
Dunn, David
Ess, Kevin C.
论文数: 0引用数: 0
h-index: 0
机构:
Vanderbilt Univ, Ctr Med, Dept Pediat, Div Pediat Neurol, Nashville, TN 37232 USAUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
Ess, Kevin C.
Hook, Dena
论文数: 0引用数: 0
h-index: 0
机构:
TB Sclerosis Alliance, Silver Spring, MD USAUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
Hook, Dena
King, Bryan H.
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h-index: 0
机构:
Univ Washington, Dept Psychiat & Behav Sci, Seattle, WA 98195 USA
Seattle Childrens Hosp, Seattle, WA USAUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
King, Bryan H.
Sahin, Mustafa
论文数: 0引用数: 0
h-index: 0
机构:
Boston Childrens Hosp, FM Kirby Ctr Neurosci, Dept Neurol, Boston, MA USAUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa
Sahin, Mustafa
Jansen, Anna
论文数: 0引用数: 0
h-index: 0
机构:
VUB, Dept Publ Hlth, UZ Brussel, Pediat Neurol Unit, Brussels, BelgiumUniv Cape Town, Div Child & Adolescent Psychiat, Dept Psychiat & Mental Hlth, ZA-7700 Cape Town, South Africa