A Case of Oral Lichen Planus Preceding the Diagnosis of Good Syndrome

被引:0
作者
Fastner, Suzanne L. [1 ]
Clarke, Jennie T. [2 ]
机构
[1] Med Coll Wisconsin, Dermatol, Milwaukee, WI USA
[2] Univ Utah Sch Med, Dermatol, Salt Lake City, UT 84132 USA
关键词
cyclosporine; pure red cell aplasia; common variable immunodeficiency; hypogammaglobinemia; thymoma; oral lichen planus; good syndrome;
D O I
10.7759/cureus.64609
中图分类号
R5 [内科学];
学科分类号
1002 ; 100201 ;
摘要
Good syndrome (GS) is a rare condition characterized by thymoma and immune deficiency with a poorly understood mechanism in which patients have reduced immunoglobulin levels and circulating B-cells along with impaired T-cell function. GS is often accompanied by autoimmune and inflammatory conditions, and in this report, we present a case of refractory oral lichen planus (OLP) preceding the diagnosis of GS. In this case, a patient with a history of OLP was diagnosed with GS and common variable immunodeficiency (CVID) following thymectomy and was treated with intravenous immunoglobin (IVIG). Additionally, he was found to have pure red cell aplasia managed with cyclosporine. His oral symptoms worsened, and he presented to dermatology. Treatment was initiated with topical clobetasol and tacrolimus for his OLP, and fluconazole was started for concomitant oral candidiasis. His OLP has remained under satisfactory control with this regimen; however, he requires close surveillance for malignancy given his increased risk of oral squamous cell carcinoma (OSCC) with immunosuppression and active OLP. Although rare, clinicians should be aware of GS and its association with erosive OLP along with the heightened risk of infection in these patients.
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页数:4
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