Middle Ear Fibrosis Contributes to Hearing Loss in Patients With Myhre Syndrome

被引:1
作者
Tayara, Alia [1 ]
Hendon, Laura G. [2 ,3 ]
Barrera, Shelby C. [4 ]
Carron, Jeffrey D. [4 ]
机构
[1] Univ Mississippi, Med Ctr, Sch Med, Jackson, MS USA
[2] Univ Mississippi, Med Ctr, Dept Pediat, Div Med Genet, Jackson, MS USA
[3] Univ Mississippi, Med Ctr, OBGYN, Jackson, MS USA
[4] Univ Mississippi, Med Ctr, Dept Otolaryngol & Commun Sci, 2500 North State St, Jackson, MS 39216 USA
关键词
conductive hearing loss; hearing loss; middle ear; otitis media; otolaryngology; pediatrics; MUTATIONS;
D O I
10.1177/01455613241256474
中图分类号
R76 [耳鼻咽喉科学];
学科分类号
100213 ;
摘要
Myhre syndrome (MS) is a rare genetic condition that presents with multiple genetic anomalies including cleft lip and palate and Eustachian tube dysfunction. These patients are at a high risk for airway scarring from intubation and mucosal inflammation. Hearing loss (conductive or mixed, of varying severity) is a common comorbidity in these patients, the exact etiology of which is still unclear. We present the cases of 2 unrelated children with MS who suffered progressive mixed hearing loss from fibrosis and obliteration of the middle ear spaces. Both patients had multiple sets of ear tubes that demonstrated early extrusion. The older patient underwent bone conduction implantation at age 11 which resulted in dramatic improvement of speech recognition and interactive skills. The other younger patient demonstrates a similar trajectory but has not yet undergone implantation. Otolaryngologists should take a cautious approach to surgery of the eardrum and middle ear to avoid unnecessary induction of fibrosis in this susceptible patient population. These cases highlight a newly described etiology for hearing loss and suggest a benefit to bone conduction implantation.
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