Incidentally findings of bilateral giant adrenal myelolipoma: Case report

被引:1
作者
Yang, Qin [1 ,2 ]
Zhu, Qiang [1 ]
You, Yuekai [1 ]
Li, Mingzhen [1 ]
Zhang, Kun [1 ]
机构
[1] Fujian Med Univ, Fuzhou Gen Hosp 1, Dept Gen Surg, Fuzhou, Peoples R China
[2] Xinjiang Uyghur Autonomous Reg Changji Hui Autonom, Dept Gen Surg, Changji, Xinjiang, Peoples R China
来源
INTERNATIONAL JOURNAL OF SURGERY CASE REPORTS | 2024年 / 122卷
关键词
Giant tumor; Adrenal gland neoplasms; Myelolipoma; Adrenal insufficiency; Radiological diagnosis; Case report; TUMORS;
D O I
10.1016/j.ijscr.2024.110045
中图分类号
R61 [外科手术学];
学科分类号
摘要
Introduction and importance: Adrenal myelolipoma (AML) is a rare, benign neoplasm of the adrenal gland often found incidentally during medical examinations for unrelated conditions. This case study presents a 39-year-old male patient with a particularly large AML, weighing 11 kg upon surgical removal, potentially making it the largest documented tumor in medical literature. Case presentation: A 39-year-old male presenting with abdominal distension and clinical manifestations of Cushing syndrome was discovered to have sizable adrenal masses. Initial pre-operative fine-needle aspiration biopsy indicated lipogenic tumors, however, subsequent post-operative pathological analysis revealed the presence of adrenal myelolipoma. Following surgery, the patient developed an adrenal crisis but responded well to glucocorticoid therapy and made a successful recovery. Clinical discussion: In contrast to previously documented instances, the present case potentially the most extensive case of its kind reported thus far. AML is an uncommon benign tumor of the adrenal gland, with diagnostic and therapeutic challenges arising from its resemblance to other adrenal neoplasms. Owing to the inherent limitations of fine needle biopsy and the propensity for misdiagnosis, the adrenal origin of the tumor was not initially considered, leading to postoperative adrenal crisis in the patient. Conclusion: AML, a rare tumor, poses challenges in accurate diagnosis. Comprehensive imaging studies are essential to differentiate it from other neoplasms. Rigorous preoperative and postoperative pathological evaluations are crucial to avoid diagnostic errors. Additionally, thorough endocrinological assessments before and after surgery are imperative for early detection and management of any associated endocrine abnormalities.
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页数:4
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