Gynecologic perivascular epithelioid cell tumors (PEComas): a review of recent evidence

被引:5
作者
Levin, Gabriel [1 ]
Capella, Mariana Pilon [2 ]
Meyer, Raanan [3 ]
Brezinov, Yoav [4 ]
Gotlieb, Walter H. [1 ]
机构
[1] McGill Univ, Jewish Gen Hosp, Dept Gynecol Oncol, Montreal, PQ, Canada
[2] Brazilian Inst Canc Control, Dept Oncol, Sao Paulo, SP, Brazil
[3] Cedars Sinai Med Ctr, Dept Obstet & Gynecol, Div Minimally Invas Gynecol Surg, Los Angeles, CA USA
[4] McGill Univ, Expt Surg, Montreal, PQ, Canada
关键词
PEComa; mTOR; Gynecologic oncology; Surgery; Rare disease; TUBEROUS SCLEROSIS; NEOPLASM PECOMA; MTOR INHIBITOR; SOFT-TISSUE; SIROLIMUS; ANGIOMYOLIPOMA; TEMSIROLIMUS; THERAPY; UTERUS;
D O I
10.1007/s00404-024-07510-5
中图分类号
R71 [妇产科学];
学科分类号
100211 ;
摘要
Gynecologic perivascular epithelioid cell (PEC) tumors, or 'PEComas,' represent a rare and intriguing subset of tumors within the female reproductive tract. This systematic literature review aims to provide an updated understanding of gynecologic PEComas based on available literature and data. Although PEComa is rare, there are varied tumor-site presentations across gynecologic organs, with uterine PEComas being the most prevalent. There is scarce high-quality literature regarding gynecologic PEComa, and studies on malignant PEComa underscore the challenges in diagnosis. Among the diverse mutations, mTOR alterations are the most prominent. Survival analysis reveals a high rate of local recurrence and metastatic disease, which commonly affects the lungs. Treatment strategies are limited, however mTOR inhibitors have pivotal role when indicated and chemotherapy may also be used. with some cases demonstrating promising responses. The paucity of data underscores the need for multicentric studies, an international registry for PEComas, and standardized reporting in case series to enhance clinical and pathological data.
引用
收藏
页码:2381 / 2386
页数:6
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